Go to JCI Insight
  • About
  • Editors
  • Consulting Editors
  • For authors
  • Publication ethics
  • Publication alerts by email
  • Advertising
  • Job board
  • Contact
  • Clinical Research and Public Health
  • Current issue
  • Past issues
  • By specialty
    • COVID-19
    • Cardiology
    • Gastroenterology
    • Immunology
    • Metabolism
    • Nephrology
    • Neuroscience
    • Oncology
    • Pulmonology
    • Vascular biology
    • All ...
  • Videos
    • Conversations with Giants in Medicine
    • Video Abstracts
  • Reviews
    • View all reviews ...
    • Complement Biology and Therapeutics (May 2025)
    • Evolving insights into MASLD and MASH pathogenesis and treatment (Apr 2025)
    • Microbiome in Health and Disease (Feb 2025)
    • Substance Use Disorders (Oct 2024)
    • Clonal Hematopoiesis (Oct 2024)
    • Sex Differences in Medicine (Sep 2024)
    • Vascular Malformations (Apr 2024)
    • View all review series ...
  • Viewpoint
  • Collections
    • In-Press Preview
    • Clinical Research and Public Health
    • Research Letters
    • Letters to the Editor
    • Editorials
    • Commentaries
    • Editor's notes
    • Reviews
    • Viewpoints
    • 100th anniversary
    • Top read articles

  • Current issue
  • Past issues
  • Specialties
  • Reviews
  • Review series
  • Conversations with Giants in Medicine
  • Video Abstracts
  • In-Press Preview
  • Clinical Research and Public Health
  • Research Letters
  • Letters to the Editor
  • Editorials
  • Commentaries
  • Editor's notes
  • Reviews
  • Viewpoints
  • 100th anniversary
  • Top read articles
  • About
  • Editors
  • Consulting Editors
  • For authors
  • Publication ethics
  • Publication alerts by email
  • Advertising
  • Job board
  • Contact
Axonally derived matrilin-2 induces proinflammatory responses that exacerbate autoimmune neuroinflammation
Anna Jonas, … , Helmut Butzkueven, Melissa Gresle
Anna Jonas, … , Helmut Butzkueven, Melissa Gresle
Published October 20, 2014
Citation Information: J Clin Invest. 2014;124(11):5042-5056. https://doi.org/10.1172/JCI71385.
View: Text | PDF
Research Article Neuroscience

Axonally derived matrilin-2 induces proinflammatory responses that exacerbate autoimmune neuroinflammation

  • Text
  • PDF
Abstract

In patients with multiple sclerosis (MS) and mice with experimental autoimmune encephalomyelitis (EAE), inflammatory axonal injury is a major determinant of disability; however, the drivers of this injury are incompletely understood. Here, we used the EAE model and determined that the extracellular matrix protein matrilin-2 (MATN2) is an endogenous neuronal molecule that is regulated in association with inflammatory axonal injury. Compared with WT mice, mice harboring a deletion of Matn2 exhibited reduced disease severity and axon damage following induction of EAE. Evaluation of neuron-macrophage cocultures revealed that exogenous MATN2 specifically signals through TLR4 and directly induces expression of proinflammatory genes in macrophages, promoting axonal damage. Moreover, the MATN2-induced proinflammatory response was attenuated greatly in macrophages from Myd88 KO mice. Examination of brain sections from patients with MS revealed that MATN2 is expressed in lesions but not in normal-appearing white matter. Together, our results indicate that MATN2 is a deleterious endogenous neuroaxonal injury response signal that activates innate immune cells and could contribute to early axonal damage in CNS inflammatory diseases like MS.

Authors

Anna Jonas, Stefan Thiem, Tanja Kuhlmann, Raimund Wagener, Attila Aszodi, Cameron Nowell, Karin Hagemeier, Louise Laverick, Victoria Perreau, Vilija Jokubaitis, Ben Emery, Trevor Kilpatrick, Helmut Butzkueven, Melissa Gresle

×

Figure 2

MATN2 is expressed in neurons and is increased in EAE motor cortex.

Options: View larger image (or click on image) Download as PowerPoint
MATN2 is expressed in neurons and is increased in EAE motor cortex.
(A) ...
(A) Labeling for MATN2 or colabeling for MATN2 and NeuN (pan-neuronal nuclear marker) in the frontal cortices of healthy mice. Scale bar: 100 μm (left); 50 μm (right); 12.5 μm (inset). (B) MATN2 IHC labeling in the human frontal cortex. Scale bar: 50 μm; 25 μm (inset). (C) Confocal images showing colabeling for MATN2, NeuN, and giantin in the frontal cortices of healthy mice. Scale bar: 10 μm. (D) Labeling for MATN2 in the frontal cortices of healthy mice and EAE mice. Scale bar: 50 μm. (E) Denaturing immunoblot analysis reveals increase in MATN2 protein in the frontal cortices of EAE mice (day 21, grade 3) compared with healthy controls. (F) Matn2 gene expression (mean ± SEM, qRT-PCR) in the motor cortices of EAE mice (day 21) is associated with disease score and specific for the frontal cortex region (n = 4–6 per group). ***P < 0.001, 1-way ANOVA/2-way ANOVA.

Copyright © 2025 American Society for Clinical Investigation
ISSN: 0021-9738 (print), 1558-8238 (online)

Sign up for email alerts